Congenital Bilateral Dacryocystocele with Nasal Pyriform Aperture Stenosis
Keywords:Congenital Dacryocystocele, Nasal Pyriform Aperture Stenosis, Congenital Anomalies, Choanal Stenosis
Congenital bilateral dacryocystocele with concomitant congenital nasal pyriform aperture stenosis is a very rare case we seen in the paediatric age group. We report a case referred by the paediatric department to rule out choanal stenosis. The referring department had difficulty to insert a feeding tube to the patient. Nose and throat examination showed reduce misting on cold spatula test and unable to introduce nasoendoscope into both nostrils, which indicates obstruction. Radiological investigation revealed as congenital dacryocystocele with nasal pyriform aperture stenosis. The patient was managed surgically with good recovery.
Wong RK, Vander Veen DK. Presentation and management of congenital dacryocystocele. Pediatrics. 2008; 122(5):e1108-12.
Hengerer AS, Brickman TM, Jeyakumar A: Choanal atresia: embryologic analysis and evolution of treatment, a 30-year experience. Laryngoscope. 2008; 118:862-866.
Thomas EM, Gibikote S, Panwar J, Mathew J: Congenital nasal pyriform aperture stenosis: a rare cause of nasal airway obstruction in a neonate. Indian J Radiol Imaging. 2010; 20:266-268.
Brachlow A, Schwartz RH, Bahadori RS. Intranasal mucocele of the nasolacrimal duct: an important cause of neonatal nasal obstruction. Clinical Pediatrics. 2004; 43(5):479-81.
Calcaterra VE, Annino DJ, Carter BL, Woog JJ. Congenital nasolacrimal duct cysts with nasal obstruction. Otolaryngology-Head and Neck Surgery. 1995; 113(4):481-4.
Jones LT, Wobig JL. Surgery of the eyelids and lacrimal systems. Birmingham: Aesculapius. 1976; p162-4.
Cassady JV. Development anatomy of the nasolacrimal duct. Arch Opthalmology. 1952; 47(2):141-158.
John PR, Boldt D. Bilateral congenital nasolacrimal sac mucoceles with nasal extension. Pediatric Radiology. 1990; 20:285-286.
Veleva N, Chernodrinska V, Mladenov O. Bilateral congenital dacryocystocele-a case report. Biomed Res. 2018; 29(10):2134–5.
Pujari A. Congenital dacryocystocele. BMJ Case Rep. 2016; 2016.
Krishnamoorthy, M, Umbaik, N, Mohamad, H, Zaidin, A. Congenital nasal pyriform aperture stenosis: a rare condition treated successfully by expectant management. Pediatria i Medycyna Rodzinna. 2020; 16(1),113–117.
Ey EH, Han BK, Towbin RB, Jaun WK. Bony inset stenosis as a cause of nasal airway obstruction. Radiology. 1988; 168:477-479.
Brown OE, Myer CM, Manning SC. Congenital nasal pyriform aperture stenosis. Laryngoscope. 1989; 99(1):86-91.
Arlis H, Ward RF. Congenital nasal pyriform aperture stenosis: isolated abnormality vs developmental field defect. Arch Otolaryngology Head and Neck Surgery. 1992; 118(9):989-991.
Lo FS, Lee YJ, Lin SP, Shen EY, Huang JK, Lee KS. Solitary maxillary central incisor and congenital nasal pyriform aperture stenosis. Eur J pediatr. 1998; 157(1):39-44.
Rollins N, Booth T, Biavati M. Case 40: Congenital pyriform aperture stenosis. Radiology. 2001; 221(2):392-4.
Cavazza S, Laffi GL, Lodi L, Tassinari G, Dall'Olio D. Congenital dacryocystocele: diagnosis and treatment. Acta Otorhinolaryngol Ital. 2008 Dec; 28(6):298-301.
Bachelard-Serra M, Chau C, Farinetti A, Roman S, Triglia JM, Nicollas R. Prenatal diagnosis of congenital dacryocystocele. Int J Pediatr Otorhinolaryngol. 2013; 77(5):847-9.
Raslan OA, Ozturk A, Pham N, Chang J, Strong EB, Bobinski M. A comprehensive review of cross-sectional imaging of the nasolacrimal drainage apparatus: What radiologists need to know. Am J Roentgenol. 2019; 213(6):1331–40.
Lee JJ, Bent JP, Ward RF. Congenital nasal pyriform aperture stenosis: non-surgical management and long-term analysis. International Journal of Pediatric Otorhinolaryngology. 2001; 60(2):167-71.
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